Pubertal androgenization and gonadal histology in two 46,XY adolescents with NR5A1 mutations and predominantly female phenotype at birth

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منابع مشابه

Pubertal androgenization and gonadal histology in two 46,XY adolescents with NR5A1 mutations and predominantly female phenotype at birth.

OBJECTIVE Most patients with NR5A1 (SF-1) mutations and poor virilization at birth are sex-assigned female and receive early gonadectomy. Although studies in pituitary-specific Sf-1 knockout mice suggest hypogonadotropic hypogonadism, little is known about endocrine function at puberty and on germ cell tumor risk in patients with SF-1 mutations. This study reports on the natural course during p...

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New NR5A1 mutations and phenotypic variations of gonadal dysgenesis

Mutations in NR5A1 have been reported as a frequent cause of 46,XY disorders of sex development (DSD) associated to a broad phenotypic spectrum ranging from infertility, ambiguous genitalia, anorchia to gonadal dygenesis and female genitalia. Here we present the clinical follow up of four 46,XY DSD patients with three novel heterozygous mutations in the NR5A1 gene leading to a p.T40P missense m...

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Gonad Histology and Gonadosomatic Index Variations during Gonadal Development of Wild Female Tenualosa ilisha

Hilsa shad (Tenualosa ilisha) is an anadromous species which has reproductive migration from the Persian Gulf to the river. Morphological properties and histological changes in oocyte of Hilsa shad in two different environments (salt water and fresh water in Khuzestan province) were studied with respect to its reproductive cycle. Twenty fish samples with average weight of 830.75±3.25 ...

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Identification of novel SRY mutations and SF1 (NR5A1) changes in patients with pure gonadal dysgenesis and 46,XY karyotype.

Primary amenorrhea due to 46,XY disorders of sexual development (DSD) is complex with the involvement of several genes. Karyotyping of such patients is important as they may develop dysgerminoma and molecular analysis is important to identify the underlying mechanism and explore the cascade of events occurring during sexual development. The present study was undertaken for the genetic analysis ...

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ژورنال

عنوان ژورنال: European Journal of Endocrinology

سال: 2012

ISSN: 0804-4643,1479-683X

DOI: 10.1530/eje-11-0392